Academic Journal
Congenital urethrovaginal fistula associated with imperforate hymen causing fetal urinary ascites and abdominal cystic lesions: A case report and literature review
| Title: | Congenital urethrovaginal fistula associated with imperforate hymen causing fetal urinary ascites and abdominal cystic lesions: A case report and literature review |
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| Authors: | Koichi Ohno, Tatsuo Nakaoka, Yuichi Takama, Atsushi Higashio, Kenji Santo, Akihiro Yoneda |
| Source: | Journal of Pediatric Surgery Case Reports, Vol 3, Iss 2, Pp 48-52 (2015) |
| Publisher Information: | Elsevier, 2015. |
| Publication Year: | 2015 |
| Collection: | LCC:Pediatrics LCC:Surgery |
| Subject Terms: | Urethrovaginal fistula, Imperforate hymen, Urinary ascites, Pediatrics, RJ1-570, Surgery, RD1-811 |
| More Details: | A primipara presented to our hospital due to fetal ascites, bilateral hydronephrosis and hydrometrocolpos. The female baby had two giant abdominal cysts, a single atrium and foot polydactyly. Absence of the vaginal orifice was noticed, and the hymen was broken through; the left cyst collapsed after fluid drainage. The right cyst was punctured and drained, which improved the hydronephrosis. Contrast imaging showed medium pouring into the abdominal cavity via the uterine tube; the right cyst was a 6 × 5 cm closed cavity. Vaginal uroplania persisted even after hospital discharge. At the age of 4 years, cystoscopy showed a fistulous opening on the urethra 5 mm distal from the internal urethral orifice. A catheter inserted via the opening was found in the vagina. In our case, urine poured into the abdominal cavity through the fistula and uterine tube; following obstruction of the uterine tube, giant hydrometrocolpos and hydrosalpinx appeared. Three cases of congenital urethrovaginal fistula (CUVF) with imperforate hymen have been reported. A remnant of communication between the uterovaginal primordium and urogenital sinus may be responsible for CUVF. |
| Document Type: | article |
| File Description: | electronic resource |
| Language: | English |
| ISSN: | 2213-5766 |
| Relation: | http://www.sciencedirect.com/science/article/pii/S2213576614001705; https://doaj.org/toc/2213-5766 |
| DOI: | 10.1016/j.epsc.2014.11.019 |
| Access URL: | https://doaj.org/article/7b2acc55a40a40ba87afa31d6b76aefb |
| Accession Number: | edsdoj.7b2acc55a40a40ba87afa31d6b76aefb |
| Database: | Directory of Open Access Journals |
| ISSN: | 22135766 |
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| DOI: | 10.1016/j.epsc.2014.11.019 |
| Published in: | Journal of Pediatric Surgery Case Reports |
| Language: | English |